TY - JOUR
T1 - Current Standards and Future Directions of Duchenne Muscular Dystrophy Respiratory Care
T2 - The PPMD Italy Meeting Report
AU - the PPMD Respiratory Group
AU - Racca, Fabrizio
AU - Finder, Jonathan D.
AU - Mercuri, Eugenio
AU - Vianello, Andrea
AU - Chatwin, Michelle
AU - Amaddeo, Alessandro
AU - Crescimanno, Grazia
AU - Trucco, Federica
AU - Sheehan, Daniel W.
AU - Barberis, Luigi
AU - Buccella, Filippo
AU - Wolff, Jodi
AU - Katz, Sherri L.
AU - Birnkrant, David J.
AU - Barberis, Luigi
AU - Birnkrant, David J.
AU - Black, Jane
AU - Buccella, Filippo
AU - Chatwin, Michelle
AU - Crescimanno, Grazia
AU - De Angelis, Fernanda
AU - De Rose, Cristina
AU - Di Cicco, Maria Elisa
AU - Croci, Massimo
AU - Fabiano, Alessia
AU - Ferrari, Giovanni
AU - Filippelli, Marco
AU - Finder, Jonathan D.
AU - Fiorentino, Giuseppe
AU - Fiorito, Valentina
AU - Katz, Sherri L.
AU - Kupfer, Oren
AU - Mercuri, Eugenio
AU - Montagnini, Luigi
AU - Pavone, Martino
AU - Pettinari, Lucia
AU - Rao, Fabrizio
AU - Ribolla, Fulvia
AU - Sheehan, Daniel W.
AU - Shell, Richard
AU - Trucco, Federica
AU - Vianello, Andrea
AU - Zinnarello, Clara
AU - Zito, Ilaria
AU - Wolff, Jodi
N1 - Publisher Copyright:
© 2025 The Author(s). Pediatric Pulmonology published by Wiley Periodicals LLC.
PY - 2025/5
Y1 - 2025/5
N2 - Objective: This report summarizes key discussions from the meeting “Current Standards and Future Directions of Respiratory Assessment and Management of Duchenne Muscular Dystrophy (DMD),” organized by Parent Project Muscular Dystrophy (PPMD) Italy and the United States to address current challenges and opportunities in DMD respiratory care. Methods: The meeting brought together researchers, clinicians, and patient advocates who shared experiences, discussed advancements in DMD respiratory management, and identified areas of debate that require further research. Results: The speakers emphasized routine assessment of pulmonary function and of breathing during sleep to achieve timely diagnosis of respiratory complications. Therapeutic discussions focused on airway clearance and assisted ventilation, highlighting noninvasive ventilation (NIV) as the preferred modality, even for advanced respiratory failure. The respiratory implications of new pharmacological therapies were discussed. The speakers endorsed the importance of cardiorespiratory outcomes in assessments of drug efficacy. To assess a drug's clinical impact and to define current respiratory phenotypes, the trajectory of the absolute value of forced vital capacity (FVC) was proposed as a potentially better parameter than FVC percent predicted, which is favored in current drug studies. In regard to management of acute respiratory failure and perioperative situations, standards of care and areas needing future research were identified. Conclusion: In this meeting, many points of consensus emerged, as well as areas requiring further research. The necessity to involve patients and their families in all aspects of respiratory care was emphasized, as well as the need for patient centered outcomes in medical decision making and research.
AB - Objective: This report summarizes key discussions from the meeting “Current Standards and Future Directions of Respiratory Assessment and Management of Duchenne Muscular Dystrophy (DMD),” organized by Parent Project Muscular Dystrophy (PPMD) Italy and the United States to address current challenges and opportunities in DMD respiratory care. Methods: The meeting brought together researchers, clinicians, and patient advocates who shared experiences, discussed advancements in DMD respiratory management, and identified areas of debate that require further research. Results: The speakers emphasized routine assessment of pulmonary function and of breathing during sleep to achieve timely diagnosis of respiratory complications. Therapeutic discussions focused on airway clearance and assisted ventilation, highlighting noninvasive ventilation (NIV) as the preferred modality, even for advanced respiratory failure. The respiratory implications of new pharmacological therapies were discussed. The speakers endorsed the importance of cardiorespiratory outcomes in assessments of drug efficacy. To assess a drug's clinical impact and to define current respiratory phenotypes, the trajectory of the absolute value of forced vital capacity (FVC) was proposed as a potentially better parameter than FVC percent predicted, which is favored in current drug studies. In regard to management of acute respiratory failure and perioperative situations, standards of care and areas needing future research were identified. Conclusion: In this meeting, many points of consensus emerged, as well as areas requiring further research. The necessity to involve patients and their families in all aspects of respiratory care was emphasized, as well as the need for patient centered outcomes in medical decision making and research.
KW - Duchenne muscular dystrophy
KW - anesthesia
KW - mechanical insufflation-exsufflation
KW - new therapies
KW - noninvasive ventilation
KW - outcome measures
KW - respiratory insufficiency
UR - https://www.scopus.com/pages/publications/105011287443
U2 - 10.1002/ppul.71113
DO - 10.1002/ppul.71113
M3 - Article
AN - SCOPUS:105011287443
SN - 8755-6863
VL - 60
JO - Pediatric Pulmonology
JF - Pediatric Pulmonology
IS - 5
M1 - e71113
ER -